Abstract
For the purpose of observing the therapeutic benefit of protease inhibitors for progressive muscular dystrophy, a large quantity of doses of leupeptin of 10 mg/kg/day and 50 mg/kg/day were administered i.p. to male chickens afflicted with hereditary muscular dystrophy (line 413) for 4 months starting on the 7th day ex ovo. No clinical improvement was identified in physical ability as a result of the examination by flip test, and creatine kinase (CK) values. The number of necrotic fibers in the pectoralis superficialis (PS) muscle which is known to be preferentially damaged in dystrophic chicken, did not decrease significantly in the birds treated with 10 mg leupeptin/kg/day (number of necrotic fibers; 47.7/mm2) and 50 mg/kg/day (46.4/mm2) as compared to that of the untreated ones (43.2/mm2). A morphometric analysis of fiber diameter distribution also showed no statistical difference between the treated and untreated birds. In the second group, 10 mg leupeptin/kg and a combination of leupeptin and bestatin of 10 mg/kg each were injected directly into the left lower half of the PS muscle three times a week for 4 months. Necrotic fibers were still present in the injected site, remote area of the left upper PS muscle treated with leupeptin (52.7/mm2), leupeptin and bestatin (52.2/mm2), and contralateral right upper PS muscle (41.6 and 53.5/mm2, respectively). The number of necrotic fibers in treated muscles was again not significantly different from that in untreated dystrophic ones (39.6/mm2). In fiber diameter analysis, no statistical difference was recognized between the treated and untreated dystrophic muscles.
MeSH Terms
Aminopeptidases/antagonists & inhibitors
Animals
Chickens
Creatine Kinase/blood
Drug Therapy, Combination
Leucine/analogs & derivatives,therapeutic use
Leupeptins/therapeutic use
Male
Muscles/pathology
Muscular Dystrophy, Animal/drug therapy,pathology
Necrosis
Oligopeptides/therapeutic use
Chemicals
Leupeptins
Oligopeptides
Creatine Kinase
Aminopeptidases
Leucine
ubenimex
Authors & Affiliations
4 authors, click to expand affiliations / ORCID
Nonaka I
Ishiura S
Takagi A
Sugita H
References (28)
28 references, click to expand
-
Muscular dystrophy: inhibition of degeneration in vivo with protease inhibitors.
Science. 1978 Apr 7;200(4337):50-1
PMID: 635570
-
Inhibitions by E-64 derivatives of rat liver cathepsin B and cathepsin L in vitro and in vivo.
J Biochem. 1980 Dec;88(6):1805-11
PMID: 7462205
-
T-tubule endocytosis in dystrophic chicken muscle and its relation to muscle fiber degeneration.
Acta Neuropathol. 1979 Oct;48(1):31-8
PMID: 506688
-
Intracytoplasmic vacuoles in alpha W fibers of dystrophic chicken muscle--probable early pathologic event initiates massive fiber necrosis.
Acta Neuropathol. 1981;55(3):173-81
PMID: 7349576
-
In vivo effects of protease inhibitors on chickens with hereditary muscular dystrophy.
J Clin Invest. 1981 Apr;67(4):969-74
PMID: 7204579
-
Delayed degeneration of dystrophic and normal muscle cell cultures treated with pepstatin, leupeptin, and antipain.
Exp Neurol. 1976 Mar;50(3):649-57
PMID: 1253868
-
Elevated activity of a neutral proteinase in human muscular dystrophy.
Biochem Med. 1980 Dec;24(3):238-43
PMID: 7025835
-
Inhibition of epoxide derivatives on chicken calcium-activated neutral protease (CANP) in vitro and in vivo.
J Biochem. 1980 Jan;87(1):339-41
PMID: 6987210
-
Biological activities of leupeptins.
J Antibiot (Tokyo). 1969 Nov;22(11):558-68
PMID: 4243683
-
Relevance of genetic animal models of muscular dystrophy to human muscular dystrophies.
Ann N Y Acad Sci. 1979;317:409-30
PMID: 289321
-
Leupeptins, new protease inhibitors from Actinomycetes.
J Antibiot (Tokyo). 1969 Jun;22(6):283-6
PMID: 5810993
-
Ca-activated neutral protease and its inhibitors: in vitro effect on intact myofibrils.
Muscle Nerve. 1980 Jul-Aug;3(4):335-9
PMID: 6251364
-
Ultrastructural localization of calcium in normal and abnormal skeletal muscle.
Lab Invest. 1977 Jun;36(6):566-77
PMID: 17033
-
Delayed functional disability in dystrophic chickens receiving chemotherapy.
Muscle Nerve. 1979 Jan-Feb;2(1):57-67
PMID: 545142
-
Leupeptin, a protease inhibitor, decreases protein degradation in normal and diseased muscles.
Science. 1978 Feb 3;199(4328):534-6
PMID: 622552
-
Intracellular calcium accumulation in Duchenne dystrophy and other myopathies: a study of 567,000 muscle fibers in 114 biopsies.
Neurology. 1978 May;28(5):439-46
PMID: 76996
-
Suppression of calcium-induced removal of the Z-line by a thiol-protease inhibitor, E-64-c.
J Biochem. 1981 Jul;90(1):283-5
PMID: 6793567
-
Successful treatment of murine muscular dystrophy with the proteinase inhibitor leupeptin.
Proc Natl Acad Sci U S A. 1981 Dec;78(12):7742-4
PMID: 6950412
-
Treatment of mouse muscular dystrophy with the protease inhibitor pepstatin.
J Neuropathol Exp Neurol. 1978 May;37(3):263-8
PMID: 660216
-
Duchenne muscular dystrophy: plasma membrane loss initiates muscle cell necrosis unless it is repaired.
Brain. 1979 Mar;102(1):147-61
PMID: 427527
-
Therapeutic trials in muscular dystrophy. III. Studies of microbial proteinase inhibitors in murine dystrophy.
Arch Neurol. 1977 Dec;34(12):771-3
PMID: 337944
-
Studies of sarcolemmal integrity in myopathic muscle.
Neurology. 1978 Jul;28(7):670-7
PMID: 79157
-
Protein measurement with the Folin phenol reagent.
J Biol Chem. 1951 Nov;193(1):265-75
PMID: 14907713
-
Segmental fibre breakdown and defects of the plasmalemma in diseased human muscles.
Acta Neuropathol. 1975 Dec 8;33(2):129-41
PMID: 1202896
-
Altered protein synthesis and creatine kinase in breast muscle cell cultures from dystrophic chick embryos.
J Neurol Sci. 1980 May;46(2):157-68
PMID: 7381511
-
Calcium-dependent proteolysis in living cells.
Life Sci. 1981 Sep 14;29(11):1079-87
PMID: 7026951
-
Duchenne dystrophy: electron microscopic findings pointing to a basic or early abnormality in the plasma membrane of the muscle fiber.
Neurology. 1975 Dec;25(12):1111-20
PMID: 1105232
-
Major physiologic and histochemical characteristics of inherited dystrophy of the chicken.
Ann N Y Acad Sci. 1979;317:224-46
PMID: 382954