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PMID: 3839802 Published · ppublish English Journal Article Research Support, Non-U.S. Gov't Research Support, U.S. Gov't, P.H.S.

Identification of a point mutation in the adenosine deaminase gene responsible for immunodeficiency.

The Journal of clinical investigation ·Vol. 76 ·No. 2 ·1985-08-00 ·Pages 894-7

Bonthron DT, Markham AF, Ginsburg D, Orkin SH

Abstract

Deficiency of adenosine deaminase (ADA) is the cause of an autosomal recessive form of immunodeficiency. We sought to define, at a molecular level, the mutations responsible for ADA deficiency in the cell line GM-1715, derived from an immunodeficient patient. Full-length complementary DNA (cDNA) for ADA was synthesized and cloned from the cell line. Sequence analysis of the clones revealed a point mutation in codon 101 (CGG to CAG) that predicts an amino acid change from arginine to glutamine. Southern blot analysis, based on silent polymorphisms in the cDNA sequence, indicated that only one of the defective alleles of the GM-1715 line had been sequenced. The mutation that was identified appears to be responsible for the loss of function in this allele, since the predicted primary structure of the enzyme is otherwise entirely normal.

MeSH Terms
Adenosine Deaminase/genetics Alleles Base Sequence Cell Line DNA/analysis Humans Immunologic Deficiency Syndromes/enzymology,genetics Mutation Nucleoside Deaminases/genetics Polymorphism, Genetic
Chemicals
DNA Nucleoside Deaminases Adenosine Deaminase
Authors & Affiliations
4 authors, click to expand affiliations / ORCID
Bonthron D T
Markham A F
Ginsburg D
Orkin S H
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Article Info
Journal
The Journal of clinical investigation
Abbr.
J Clin Invest
ISSN
0021-9738
Published
1985-08-00
Pages
894-7
Language
English
Region
United States
NLM ID
7802877
PMCID
PMC423929
Subset
IM
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