Abstract
We have investigated the structural gene for adenosine deaminase (ADA) in a female infant with ADA deficiency associated severe combined immune deficiency (ADA-SCID) disease and her family by DNA restriction-fragment-length analysis. In this family a new ADA-specific restriction-fragment-length variant was detected, which involves a 3.2-kb deletion spanning the ADA promoter as well as the first exon. It was found that the patient, who was born to a consanguineous couple, was homozygous and both her parents and her brother were heterozygous for the deletion. No ADA-specific mRNA could be detected by hybridization in fibroblasts derived from this patient. Thus the patient was established to be homozygous for a true null ADA allele. In the light of the apparently normal development of most tissues except the lymphoid tissue the above finding directly questions the classification of ADA as a 'housekeeping' enzyme.
MeSH Terms
Adenosine Deaminase/blood,deficiency
Chromosome Deletion
Erythrocytes/enzymology
Exons
Female
Genes
Homozygote
Humans
Immunologic Deficiency Syndromes/enzymology,genetics
Infant
Leukocytes/enzymology
Male
Nucleoside Deaminases/deficiency
Promoter Regions, Genetic
RNA, Messenger/genetics
Reference Values
Transcription, Genetic
Chemicals
RNA, Messenger
Nucleoside Deaminases
Adenosine Deaminase
Authors & Affiliations
9 authors, click to expand affiliations / ORCID
Berkvens T M
Department of Human Genetics, Sylvius Laboratories, University of Leiden, The Netherlands.
Gerritsen E J
Oldenburg M
Breukel C
Wijnen J T
van Ormondt H
Vossen J M
van der Eb A J
Meera Khan P
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