Abstract
Mutations in NLRP3 (CIAS1) are identified in a continuum of related inflammatory disorders, known as cryopyrinopathies since NLRP3 codes for the protein cryopyrin. Approximately 40% of patients with classic presentation lack mutations in the coding region of NLRP3 suggesting heterogeneity or epigenetic factors. Cryopyrin is a key regulator of proinflammatory cytokine release. Therefore, variations in the NLRP3 promoter sequence may have effects on disease state in patients with cryopyrinopathies and other inflammatory diseases. In this report, we confirmed three 5'-untranslated region splice forms with two separate transcriptional start sites, and identified potential promoter regions and six new DNA promoter variants. One variant is unique to a mutation negative cryopyrinopathy patient and increases in vitro gene expression. Additional studies can now be performed to further characterize the NLRP3 promoter and sequence variants, which will lead to better understanding of the regulation of NLRP3 expression and its role in disease.
MeSH Terms
Carrier Proteins/genetics
Humans
Inflammation/genetics
Leukocytes
NLR Family, Pyrin Domain-Containing 3 Protein
Promoter Regions, Genetic/genetics
RNA Splice Sites/genetics
Chemicals
Carrier Proteins
NLR Family, Pyrin Domain-Containing 3 Protein
NLRP3 protein, human
RNA Splice Sites
Authors & Affiliations
7 authors, click to expand affiliations / ORCID
Anderson J P
Department of Emergency Medicine, Harbor-UCLA Medical Center, Torrance, CA, USA.
Mueller J L
Misaghi A
Anderson S
Sivagnanam M
Kolodner R D
Hoffman H M
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