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PMID: 16642435 Published · ppublish English Evaluation Study Journal Article Research Support, Non-U.S. Gov't

Cis- and trans-acting gene regulation is associated with osteoarthritis.

American journal of human genetics ·Vol. 78 ·No. 5 ·2006-05-00 ·Pages 793-803

Mahr S, Burmester GR, Hilke D, Göbel U, Grützkau A, Häupl T, Hauschild M, Koczan D, Krenn V, Neidel J, Perka C, Radbruch A, Thiesen HJ, Müller B

Abstract

Osteoarthritis (OA) is a complex disease of the skeleton and is associated with aging. Both environmental and genetic factors contribute to its pathogenesis. We set out to identify novel genes associated with OA, concentrating on regulatory polymorphisms allowing for differential expression. Our strategy to identify differentially expressed genes included an initial transcriptome analysis of the peripheral blood mononuclear cells of six patients with OA and six age-matched healthy controls. These were screened for allelic expression imbalances and potentially regulatory single-nucleotide polymorphisms (SNPs) in the 5' regions of the genes. To establish disease association, disparate promoter SNP distributions correlating with the differential expression were tested on larger cohorts. Our approach yielded 26 candidate genes differentially expressed between patients and controls. Whereas BLP2 and CIAS1 seem to be trans-regulated, as the absence of allelic expression imbalances suggests, the presence of allelic imbalances confirms cis-regulatory mechanisms for RHOB and TXNDC3. Interestingly, on/off-switching suggests additional trans-regulation for TXNDC3. Moreover, we demonstrate for RHOB and TXNDC3 statistically significant associations between 5' SNPs and the disease that hint at regulatory functions. Investigating the respective genes functionally will not only shed light on the disease association but will also add to the understanding of the pathogenic processes involved in OA and may point out novel therapeutic approaches.

MeSH Terms
Adult Aged Allelic Imbalance Carrier Proteins/genetics,metabolism Case-Control Studies Chondrocytes/metabolism Cohort Studies Female Gene Expression Regulation Genetic Predisposition to Disease Humans Male Membrane Proteins Middle Aged NLR Family, Pyrin Domain-Containing 3 Protein Oligonucleotide Array Sequence Analysis Osteoarthritis/genetics,metabolism Polymorphism, Single Nucleotide Promoter Regions, Genetic Thioredoxins/genetics,metabolism Transcription, Genetic rhoB GTP-Binding Protein/genetics,metabolism
Chemicals
Carrier Proteins Membrane Proteins NLR Family, Pyrin Domain-Containing 3 Protein NLRP3 protein, human NME8 protein, human TM2D1 protein, human Thioredoxins rhoB GTP-Binding Protein
Authors & Affiliations
14 authors, click to expand affiliations / ORCID
Mahr Sandra
Institute for Immunology, Rostock, Germany. Electronic address: sandra.mahr@med.uni-rostock.de.
Burmester Gerd-Rüdiger
Charité University Hospital, Medical Faculty, Humboldt University.
Hilke Dietmar
THALES IS, Berlin, Germany.
Göbel Udo
Contact Software GmbH, Bremen, Germany.
Grützkau Andreas
German Rheumatism Research Center, Berlin, Germany.
Häupl Thomas
Charité University Hospital, Medical Faculty, Humboldt University.
Hauschild Matthias
Orthopedic Surgery, Medical Faculty, University of Rostock, Rostock, Germany.
Koczan Dirk
Institute for Immunology, Rostock, Germany.
Krenn Veit
Charité University Hospital, Medical Faculty, Humboldt University.
Neidel Jasper
Orthopädie Zentrum Altona, Hamburg, Germany.
Perka Carsten
Charité University Hospital, Medical Faculty, Humboldt University.
Radbruch Andreas
German Rheumatism Research Center, Berlin, Germany.
Thiesen Hans-Jürgen
Institute for Immunology, Rostock, Germany.
Müller Brigitte
Institute for Immunology, Rostock, Germany.
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Article Info
Journal
American journal of human genetics
Abbr.
Am J Hum Genet
ISSN
0002-9297
Published
2006-05-00
Epub
2006-00-22
Pages
793-803
Language
English
Region
United States
NLM ID
0370475
PMCID
PMC1474041
Subset
IM
Corrections
CommentIn
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