Abstract
Structural anomalies of the sex chromosomes provide a means to study the location of genes responsible for sex determination. Recently, a type of sex reversal in humans, the 46,XX male, was shown to result in some cases from translocation of Y chromosome material to the X chromosome. In the present report, another type of sex reversal, the 46,XY female, is shown to result, in two cases, from small deletions of the short arm of the Y chromosome. Prometaphase chromosome analysis showed a 46,X,Yp- karyotype. Several Y chromosome-specific DNA probes were found to be deleted in the two female patients. DNA analysis showed that the two deletions were different but included a common overlapping region likely to be essential for male determination.
MeSH Terms
Chromosome Deletion
DNA/analysis
Female
Humans
Nucleic Acid Hybridization
Turner Syndrome/genetics
Y Chromosome
Authors & Affiliations
9 authors, click to expand affiliations / ORCID
Disteche C M
Casanova M
Saal H
Friedman C
Sybert V
Graham J
Thuline H
Page D C
Fellous M
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