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PMID: 941901 Published · ppublish English Journal Article Research Support, U.S. Gov't, Non-P.H.S. Research Support, U.S. Gov't, P.H.S.

Low levels of beta hexosaminidase A in healthy individuals with apparent deficiency of this enzyme.

American journal of human genetics ·Vol. 28 ·No. 4 ·1976-07-00 ·Pages 339-49

Navon R, Geiger B, Yoseph YB, Rattazzi MC

Abstract

Appreciable beta hexosaminidase A (hex A) activity has been detected in cultured skin fibroblasts and melanoma tissue from healthy individuals previously reported as having deficiency of hex A activity indistinguishable from that of patients with Tay-Sachs disease (TSD). Identification and quantitation of hex A, amounting to 3.5%-6.9% of total beta hexosaminidase activity, has been obtained by cellulose acetate gel electrophoresis, DEAE-cellulose ion-exchange chromatography, radial immunodiffusion, and radioimmunoassay. Previous family studies suggested that these individuals may be compound heterozygotes for the common mutant TSD gene and a rare (allelic) mutant gene. Thus, the postulated rate mutant gene appears to code for the expression of low amounts of hex A. Heterozygotes for the rare mutant may be indistinguishable from heterozygotes for the common TSD mutant. However, direct visualization and quantitation of hex A by the methods described may prevent false-positive prenatal diagnosis of TSD in fetuses having the incomplete hex A deficiency of the type described in the four healthy individuals.

MeSH Terms
Cells, Cultured Heterozygote Hexosamines/deficiency Humans Lipidoses/enzymology Liver/enzymology Melanoma/enzymology Skin/enzymology Skin Neoplasms/enzymology
Chemicals
Hexosamines
Authors & Affiliations
4 authors, click to expand affiliations / ORCID
Navon R
Geiger B
Yoseph Y B
Rattazzi M C
References (23)
23 references, click to expand
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Article Info
Journal
American journal of human genetics
Abbr.
Am J Hum Genet
ISSN
0002-9297
Published
1976-07-00
Pages
339-49
Language
English
Region
United States
NLM ID
0370475
PMCID
PMC1685065
Subset
IM
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