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PMID: 8690795 Published · ppublish English Journal Article Research Support, U.S. Gov't, P.H.S.

Ceruloplasmin gene expression in the murine central nervous system.

The Journal of clinical investigation ·Vol. 98 ·No. 1 ·1996-07-01 ·Pages 207-15

Klomp LW, Farhangrazi ZS, Dugan LL, Gitlin JD

Abstract

Aceruloplasminemia is an autosomal recessive disorder resulting in neurodegeneration of the retina and basal ganglia in association with iron accumulation in these tissues. To begin to define the mechanisms of central nervous system iron accumulation and neuronal loss in this disease, cDNA clones encoding murine ceruloplasmin were isolated and characterized. RNA blot analysis using these clones detected a 3.7-kb ceruloplasmin-specific transcript in multiple murine tissues including the eye and several regions of the brain. In situ hybridization of systemic tissues revealed cell-specific ceruloplasmin gene expression in hepatocytes, the splenic reticuloendothelial system and the bronchiolar epithelium of the lung. In the central nervous system, abundant ceruloplasmin gene expression was detected in specific populations of astrocytes within the retina and the brain as well as the epithelium of the choroid plexus. Analysis of primary cell cultures confirmed that astrocytes expressed ceruloplasmin mRNA and biosynthetic studies revealed synthesis and secretion of ceruloplasmin by these cells. Taken together these results demonstrate abundant cell-specific ceruloplasmin expression within the central nervous system which may account for the unique clinical and pathologic findings observed in patients with aceruloplasminemia.

MeSH Terms
Amino Acid Sequence Animals Brain/metabolism Ceruloplasmin/biosynthesis,deficiency,genetics Cloning, Molecular DNA, Complementary Eye/metabolism Gene Expression Genes, Recessive In Situ Hybridization Metabolism, Inborn Errors/etiology Mice Molecular Sequence Data Neuroglia/cytology,metabolism Neurons/cytology,metabolism Sequence Homology, Amino Acid Tissue Distribution
Chemicals
DNA, Complementary Ceruloplasmin
Authors & Affiliations
4 authors, click to expand affiliations / ORCID
Klomp L W
Edward Mallinckrodt Department off Pediatrics, Washington University School of Medicine, St. Louis, Missouri 63110, USA.
Farhangrazi Z S
Dugan L L
Gitlin J D
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Article Info
Journal
The Journal of clinical investigation
Abbr.
J Clin Invest
ISSN
0021-9738
Published
1996-07-01
Pages
207-15
Language
English
Region
United States
NLM ID
7802877
PMCID
PMC507418
Subset
IM
Grants
NHLBI NIH HHS · HL-41536 · United States
Databases
GENBANK
U49430
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