Abstract
Inherited predisposition to phaeochromocytoma is seen in multiple endocrine neoplasia type 2 syndromes, von Hippel-Lindau (VHL) disease, and neuro-fibromatosis type 1. In addition familial phaeochromocytoma alone has been reported. To investigate the genetic basis for familial phaeochromocytoma alone, we screened three affected kindreds for mutations in the RET proto-oncogene and the VHL tumour suppressor gene. We did not detect MEN 2 associated RET mutations in any family, but missense VHL gene mutations (V155L and R238W) were identified in two kindreds with no clinical evidence of VHL disease. Patients with familial, multiple, or early onset phaeochromocytoma should be investigated for germline VHL and RET gene mutations as the molecular diagnosis of multisystem familial cancer syndromes enables appropriate counselling and screening to be provided.
MeSH Terms
Adolescent
Adrenal Gland Neoplasms/genetics
Adult
Child
DNA Mutational Analysis
Drosophila Proteins
Female
Genes, Tumor Suppressor
Humans
Ligases
Male
Neoplasms, Multiple Primary/genetics
Neoplastic Syndromes, Hereditary/diagnosis,genetics
Pedigree
Pheochromocytoma/genetics
Point Mutation
Proteins/genetics
Proto-Oncogene Mas
Proto-Oncogene Proteins/genetics
Proto-Oncogene Proteins c-ret
Proto-Oncogenes
Receptor Protein-Tyrosine Kinases/genetics
Tumor Suppressor Proteins
Ubiquitin-Protein Ligases
Von Hippel-Lindau Tumor Suppressor Protein
von Hippel-Lindau Disease/diagnosis,genetics
Chemicals
Drosophila Proteins
MAS1 protein, human
Proteins
Proto-Oncogene Mas
Proto-Oncogene Proteins
Tumor Suppressor Proteins
Ubiquitin-Protein Ligases
Von Hippel-Lindau Tumor Suppressor Protein
Proto-Oncogene Proteins c-ret
Receptor Protein-Tyrosine Kinases
Ret protein, Drosophila
Ligases
VHL protein, human
Authors & Affiliations
7 authors, click to expand affiliations / ORCID
Crossey P A
Human Molecular Genetics Group, University of Cambridge, Department of Pathology, Addenbrooke's Hospital, UK.
Eng C
Ginalska-Malinowska M
Lennard T W
Wheeler D C
Ponder B A
Maher E R
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