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PMID: 7753829 Published · ppublish English Journal Article

Loss of Apc heterozygosity and abnormal tissue building in nascent intestinal polyps in mice carrying a truncated Apc gene.

Oshima M, Oshima H, Kitagawa K, Kobayashi M, Itakura C, Taketo M

Abstract

Mutations in the APC (adenomatous polyposis coli) gene appear to be responsible for not only familial adenomatous polyposis but also many sporadic cases of gastrointestinal cancers. Using homologous recombination in mouse embryonic stem cells, we constructed mice that contained a mutant gene encoding a product truncated at a 716 (Apc delta 716). Mendelian transmission of the gene caused most homozygous mice to die in utero before day 8 of gestation. The heterozygotes developed multiple polyps throughout the intestinal tract, mostly in the small intestine. The earliest polyps arose multifocally during the third week after birth, and new polyps continued to appear thereafter. Surprisingly, every nascent polyp consisted of a microadenoma covered with a layer of the normal villous epithelium. These microadenomas originated from single crypts by forming abnormal outpockets into the inner (lacteal) side of the neighboring villi. We carefully dissected such microadenomas from nascent polyps by peeling off the normal epithelium and determined their genotype by PCR: all microadenomas had already lost the wild-type Apc allele, whereas the mutant allele remained unchanged. These results indicate that loss of heterozygosity followed by formation of intravillous microadenomas is responsible for polyposis in Apc delta 716 intestinal mucosa. It is therefore unlikely that the truncated product interacts directly with the wild-type protein and causes the microadenomas by a dominant negative mechanism.

Related Genes
MeSH Terms
Adenoma/genetics,pathology Animals Base Sequence Blastocyst/metabolism Chimera Chromosome Deletion Codon DNA Primers Embryo, Mammalian Epithelial Cells Epithelium/pathology Female Fetal Death Gene Deletion Genes, APC Humans Intestinal Neoplasms/genetics,pathology Intestinal Polyps/genetics,pathology Mice Mice, Inbred C57BL Molecular Sequence Data Mutagenesis Polymerase Chain Reaction Pregnancy Recombination, Genetic Restriction Mapping Stem Cells
Chemicals
Codon DNA Primers
Authors & Affiliations
6 authors, click to expand affiliations / ORCID
Oshima M
Banyu Tsukuba Research Institute (Merck), Japan.
Oshima H
Kitagawa K
Kobayashi M
Itakura C
Taketo M
References (32)
32 references, click to expand
  1. Mutation and cancer: statistical study of retinoblastoma.
    Proc Natl Acad Sci U S A. 1971 Apr;68(4):820-3 PMID: 5279523
  2. The APC gene product associates with microtubules in vivo and promotes their assembly in vitro.
    Cancer Res. 1994 Jul 15;54(14):3676-81 PMID: 8033083
  3. Morphological basis of multistep process in experimental colonic carcinogenesis.
    Virchows Arch B Cell Pathol Incl Mol Pathol. 1982;41(1-2):17-37 PMID: 6134381
  4. Localization of the gene for familial adenomatous polyposis on chromosome 5.
    Nature. 1987 Aug 13-19;328(6131):614-6 PMID: 3039373
  5. Regulation of intestinal epithelial cell growth by transforming growth factor type beta.
    Proc Natl Acad Sci U S A. 1989 Mar;86(5):1578-82 PMID: 2466294
  6. A dominant mutation that predisposes to multiple intestinal neoplasia in the mouse.
    Science. 1990 Jan 19;247(4940):322-4 PMID: 2296722
  7. Genetic changes and histopathological types in colorectal tumors from patients with familial adenomatous polyposis.
    Cancer Res. 1990 Nov 15;50(22):7166-73 PMID: 1977514
  8. Homologous recombination at c-fyn locus of mouse embryonic stem cells with use of diphtheria toxin A-fragment gene in negative selection.
    Proc Natl Acad Sci U S A. 1990 Dec;87(24):9918-22 PMID: 2263643
  9. Targeted disruption of the c-src proto-oncogene leads to osteopetrosis in mice.
    Cell. 1991 Feb 22;64(4):693-702 PMID: 1997203
  10. Identification and characterization of the familial adenomatous polyposis coli gene.
    Cell. 1991 Aug 9;66(3):589-600 PMID: 1651174
  11. Identification of deletion mutations and three new genes at the familial polyposis locus.
    Cell. 1991 Aug 9;66(3):601-13 PMID: 1678319
  12. Identification of FAP locus genes from chromosome 5q21.
    Science. 1991 Aug 9;253(5020):661-5 PMID: 1651562
  13. Mutations of chromosome 5q21 genes in FAP and colorectal cancer patients.
    Science. 1991 Aug 9;253(5020):665-9 PMID: 1651563
  14. Loss of heterozygosity involving the APC and MCC genetic loci occurs in the majority of human esophageal cancers.
    Proc Natl Acad Sci U S A. 1992 Apr 15;89(8):3385-8 PMID: 1565631
  15. Germ-line mutations of the APC gene in 53 familial adenomatous polyposis patients.
    Proc Natl Acad Sci U S A. 1992 May 15;89(10):4452-6 PMID: 1316610
  16. Multiple intestinal neoplasia caused by a mutation in the murine homolog of the APC gene.
    Science. 1992 May 1;256(5057):668-70 PMID: 1350108
  17. The APC gene, responsible for familial adenomatous polyposis, is mutated in human gastric cancer.
    Cancer Res. 1992 Jun 1;52(11):3231-3 PMID: 1317264
  18. APC mutations occur early during colorectal tumorigenesis.
    Nature. 1992 Sep 17;359(6392):235-7 PMID: 1528264
  19. Targeted disruption of the mouse transforming growth factor-beta 1 gene results in multifocal inflammatory disease.
    Nature. 1992 Oct 22;359(6397):693-9 PMID: 1436033
  20. Inactivation of both APC alleles in an early stage of colon adenomas in a patient with familial adenomatous polyposis (FAP).
    Hum Mol Genet. 1992 Sep;1(6):387-90 PMID: 1338760
  21. Association between wild type and mutant APC gene products.
    Cancer Res. 1993 Jun 15;53(12):2728-31 PMID: 8389242
  22. Detailed analysis of genetic alterations in colorectal tumors from patients with and without familial adenomatous polyposis (FAP).
    Oncogene. 1993 Sep;8(9):2399-405 PMID: 8395678
  23. APC gene messenger RNA: novel isoforms that lack exon 7.
    Cancer Res. 1993 Dec 1;53(23):5589-91 PMID: 8242607
  24. Genetic identification of Mom-1, a major modifier locus affecting Min-induced intestinal neoplasia in the mouse.
    Cell. 1993 Nov 19;75(4):631-9 PMID: 8242739
  25. Dimer formation by an N-terminal coiled coil in the APC protein.
    Proc Natl Acad Sci U S A. 1993 Dec 1;90(23):11109-13 PMID: 8248216
  26. Alleles of the APC gene: an attenuated form of familial polyposis.
    Cell. 1993 Dec 3;75(5):951-7 PMID: 8252630
  27. Restriction of ocular fundus lesions to a specific subgroup of APC mutations in adenomatous polyposis coli patients.
    Cell. 1993 Dec 3;75(5):959-68 PMID: 8252631
  28. Association of the APC gene product with beta-catenin.
    Science. 1993 Dec 10;262(5140):1731-4 PMID: 8259518
  29. Association of the APC tumor suppressor protein with catenins.
    Science. 1993 Dec 10;262(5140):1734-7 PMID: 8259519
  30. Demonstration of promoter activity and alternative splicing in the region 5' to exon 1 of the APC gene.
    Cancer Res. 1994 Jun 1;54(11):2991-5 PMID: 8187087
  31. Wild-type but not mutant APC associates with the microtubule cytoskeleton.
    Cancer Res. 1994 Jul 15;54(14):3672-5 PMID: 8033082
  32. In vivo measurements in familial polyposis: kinetics and location of proliferating cells in colonic adenomas.
    Cancer Res. 1982 Oct;42(10):4280-3 PMID: 7105022
Article Info
Journal
Proceedings of the National Academy of Sciences of the United States of America
Abbr.
Proc Natl Acad Sci U S A
ISSN
0027-8424
Published
1995-05-09
Pages
4482-6
Language
English
Region
United States
NLM ID
7505876
PMCID
PMC41968
Subset
IM
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