Abstract
A patient with vitamin D dependent rickets with decreased sensitivity to 1,25-Dihydroxyvitamin D was observed. She suffered from bone pain of two years duration beginning at 12 years of age and was found to be suffering from hypocalcemia, secondary hyperparathyroidism and osteomalacia. Laboratory findings revealed normal serum 25-hydroxyvitamin D (27 ng/ml) and markedly elevated serum 1,25-dihydroxy-vitamin D (131.9 pg/ml). The hypocalcemia was refractory in spite of administration of 25,000 units of vitamin D2, but therapy with high doses of oral la-hydroxyvitamin D3 resulted in significant elevation of the serum calcium level. The clinical findings and course of the patient's disease were quite different from those of other patients with vitamin D dependent rickets reported by other authors.
MeSH Terms
Adolescent
Dihydroxycholecalciferols/blood
Female
Humans
Hydroxycholecalciferols/blood,therapeutic use
Hyperparathyroidism, Secondary/complications
Hypocalcemia/complications,drug therapy
Osteomalacia/drug therapy,etiology
Rickets/diagnosis,drug therapy
Chemicals
Dihydroxycholecalciferols
Hydroxycholecalciferols
Authors & Affiliations
8 authors, click to expand affiliations / ORCID
Kudoh T
Kumagai T
Uetsuji N
Tsugawa S
Oyanagi K
Chiba Y
Minami R
Nakao T
References (8)
8 references, click to expand
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