Home LiteratureArticle Details
PMID: 6953420 Published · ppublish English Journal Article Research Support, Non-U.S. Gov't

Genetic heterogeneity in ataxia-telangiectasia studied by cell fusion.

Jaspers NG, Bootsma D

Abstract

The effect of x-rays on the rate of semiconservative DNA replication was investigated by autoradiography in single cells obtained from normal individuals and from patients having ataxia-telangiectasia (AT). In the five AT cell strains studied, the rate of DNA synthesis was inhibited to a lesser extent that in two normal cell strains. By using this abnormal regulation of DNA replication in AT cells as a marker, an experimental procedure was developed that allowed genetic complementation analysis of AT. After Sendai virus-induced fusion of AT cells, the grains were counted over binucleate cells with both nuclei in S phase. In some cases, the inhibition of DNA synthesis caused by x-rays in the heterodikaryons was more pronounced than that in the parental homodikaryons and was comparable to that in normal binucleate cells, indicating complementation. By using this approach, the five AT cell strains that were investigated could be assigned to three complementation groups. The data suggest that extensive genetic heterogeneity exists in AT.

MeSH Terms
Ataxia Telangiectasia/genetics Cell Fusion Cells, Cultured DNA Replication/radiation effects Dose-Response Relationship, Radiation Genetic Complementation Test Humans Kinetics
Authors & Affiliations
2 authors, click to expand affiliations / ORCID
Jaspers N G
Bootsma D
References (9)
9 references, click to expand
  1. Defective excision repair of gamma-ray-damaged DNA in human (ataxia telangiectasia) fibroblasts.
    Nature. 1976 Apr 1;260(5550):444-7 PMID: 1256588
  2. Semi-conservative deoxyribonucleic acid synthesis in unirradiated and ultraviolet-irradiated xeroderma pigmentosum and normal human skin fibroblasts.
    Mutat Res. 1977 Mar;42(3):433-42 PMID: 854043
  3. A seventh complementation group in excision-deficient xeroderma pigmentosum.
    Mutat Res. 1979 Aug;62(1):183-90 PMID: 492197
  4. Ataxia telangiectasia: an inherited human disorder involving hypersensitivity to ionizing radiation and related DNA-damaging chemicals.
    Annu Rev Genet. 1979;13:291-318 PMID: 395894
  5. Unusual levels of (ADP-ribose)n and DNA synthesis in ataxia telangiectasia cells following gamma-ray irradiation.
    Nature. 1980 Oct 23;287(5784):745-7 PMID: 7432491
  6. Effect of ionizing radiation on DNA synthesis in ataxia telangiectasia cells.
    Nucleic Acids Res. 1980 Aug 25;8(16):3709-20 PMID: 7433105
  7. The rate of DNA synthesis in normal human and ataxia telangiectasia cells after exposure to X-irradiation.
    Mutat Res. 1981 Jan;80(1):221-6 PMID: 7207484
  8. Radiosensitivity in ataxia-telangiectasia: a new explanation.
    Proc Natl Acad Sci U S A. 1980 Dec;77(12):7315-7 PMID: 6938978
  9. Complement analysis of xeroderma pigmentosum variants.
    Exp Cell Res. 1981 Nov;136(1):81-90 PMID: 7297615
Article Info
Journal
Proceedings of the National Academy of Sciences of the United States of America
Abbr.
Proc Natl Acad Sci U S A
ISSN
0027-8424
Published
1982-04-00
Pages
2641-4
Language
English
Region
United States
NLM ID
7505876
PMCID
PMC346256
Subset
IM
Analysis Services
Analysis Services

Contact

No. 2 Wenbo Road, Zhangqiu District, Jinan, Shandong

Qilu Normal University · Genelibs Bioinformatics Lab

750 Shunhua Rd, Jinan

2F, Bldg F, University Science Park

Tel: 0531-88819269

WeChat Official Account

Follow our WeChat subscription account for real-time updates and the latest in medical and biological research.


Business Email

E-mail: product@genelibs.com