Abstract
Among several established mouse, rat, and Chinese hamster cell lines that were screened for cystathionine beta-synthase (CBS) activity, mouse 3T3 and Chinese hamster Don fibroblasts were found to contain no detectable activity. Somatic cell hybrids between human fibroblasts KG-7 with normal CBS activity and Don/a23TK- cells (series XXI) were examined for CBS activity and for human chromosome content. Only chromosome 21 cosegregated with CBS activity. Because the activities measured could represent either Chinese hamster or human gene products, we have prepared a new series of hybrids between Don/a23TK- cells and mutant human fibroblasts from a patient with homocystinuria due to deficiency of functional CBS mRNA. None of these (series XXV) hybrids contained detectable CBS activity, although collectively all human chromosomes were represented. Our results suggest that the human gene for CBS, called CBS, and thus for the most common form of homocystinuria, is located on chromosome 21.
MeSH Terms
Adolescent
Adult
Animals
Cell Line
Child
Child, Preschool
Chromosome Mapping
Chromosomes, Human, 21-22 and Y
Cricetinae
Cricetulus
Cystathionine beta-Synthase/genetics
Fibroblasts/enzymology
Genetic Markers
Humans
Hybrid Cells
Hydro-Lyases/genetics
Mice
Rats
Thymidine Kinase/genetics
Chemicals
Genetic Markers
Thymidine Kinase
Hydro-Lyases
Cystathionine beta-Synthase
Authors & Affiliations
3 authors, click to expand affiliations / ORCID
Skovby F
Krassikoff N
Francke U
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17 references, click to expand
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