Abstract
Crossover sites resulting from unequal recombination within the human growth hormone (GH) gene cluster that cause GH1 gene deletions and isolated GH deficiency type 1A were localized in nine patients. In eight unrelated subjects homozygous for 6.7-kilobase (kb) deletions, the breakpoints are within two blocks of highly homologous DNA sequences that lie 5' and 3' to the GH1 gene. In seven of these eight cases, the breakpoints map within a 1250-base-pair (bp) region composed of 300-bp Alu sequences of 86% homology and flanking non-Alu sequences that are 600 and 300 bp in length and are of 96% and 88% homology, respectively. In the eighth patient, the breakpoints are 5' to these Alu repeats and are most likely within a 700-bp region of 96% homologous DNA sequences. In the ninth patient homozygous for a 7.6-kb deletion, the breakpoints are contained within a 29-bp perfect repeat lying 5' to GH1 and the human chorionic somatomammotropin pseudogene (CSHP1). Together, these results indicate that the presence of highly homologous DNA sequences flanking GH1 predispose to recurrent unequal recombinational events presumably through chromosomal misalignment.
MeSH Terms
Base Sequence
Chromosome Deletion
DNA/genetics
DNA Restriction Enzymes
Deoxyribonucleases, Type II Site-Specific
Genes
Growth Disorders/genetics
Growth Hormone/deficiency,genetics
Humans
Nucleic Acid Hybridization
Repetitive Sequences, Nucleic Acid
Sequence Homology, Nucleic Acid
Chemicals
Growth Hormone
DNA
DNA Restriction Enzymes
endodeoxyribonuclease MstII
Deoxyribonucleases, Type II Site-Specific
GCCNNNNNGGC-specific type II deoxyribonucleases
Authors & Affiliations
4 authors, click to expand affiliations / ORCID
Vnencak-Jones C L
Department of Pediatrics, Vanderbilt University School of Medicine, Nashville, TN 37232.
Phillips J A
Chen E Y
Seeburg P H
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