Abstract
Cohesin enables post-replicative DNA repair and chromosome segregation by holding sister chromatids together from the time of DNA replication in S phase until mitosis. There is growing evidence that cohesin also forms long-range chromosomal cis-interactions and may regulate gene expression in association with CTCF, mediator or tissue-specific transcription factors. Human cohesinopathies such as Cornelia de Lange syndrome are thought to result from impaired non-canonical cohesin functions, but a clear distinction between the cell-division-related and cell-division-independent functions of cohesion--as exemplified in Drosophila--has not been demonstrated in vertebrate systems. To address this, here we deleted the cohesin locus Rad21 in mouse thymocytes at a time in development when these cells stop cycling and rearrange their T-cell receptor (TCR) α locus (Tcra). Rad21-deficient thymocytes had a normal lifespan and retained the ability to differentiate, albeit with reduced efficiency. Loss of Rad21 led to defective chromatin architecture at the Tcra locus, where cohesion-binding sites flank the TEA promoter and the Eα enhancer, and demarcate Tcra from interspersed Tcrd elements and neighbouring housekeeping genes. Cohesin was required for long-range promoter-enhancer interactions, Tcra transcription, H3K4me3 histone modifications that recruit the recombination machinery and Tcra rearrangement. Provision of pre-rearranged TCR transgenes largely rescued thymocyte differentiation, demonstrating that among thousands of potential target genes across the genome, defective Tcra rearrangement was limiting for the differentiation of cohesin-deficient thymocytes. These findings firmly establish a cell-division-independent role for cohesin in Tcra locus rearrangement and provide a comprehensive account of the mechanisms by which cohesin enables cellular differentiation in a well-characterized mammalian system.
MeSH Terms
Animals
Cell Cycle Proteins/genetics,metabolism
Cell Differentiation
Chromosomal Proteins, Non-Histone/deficiency,genetics,metabolism
DNA-Binding Proteins
Gene Expression Regulation
Gene Rearrangement, T-Lymphocyte/genetics
Genes, RAG-1/genetics
Mice
Nuclear Proteins/deficiency,genetics,metabolism
Phosphoproteins/deficiency,genetics,metabolism
Receptors, Antigen, T-Cell, alpha-beta/genetics,metabolism
Recombinases/metabolism
Thymus Gland/cytology,metabolism
Transcription, Genetic
Chemicals
Cell Cycle Proteins
Chromosomal Proteins, Non-Histone
DNA-Binding Proteins
Nuclear Proteins
Phosphoproteins
Rad21 protein, mouse
Receptors, Antigen, T-Cell, alpha-beta
Recombinases
cohesins
Authors & Affiliations
18 authors, click to expand affiliations / ORCID
Seitan Vlad C
Lymphocyte Development Group, MRC Clinical Sciences Centre, Imperial College London, Du Cane Road, London W12 0NN, UK.
Hao Bingtao
Tachibana-Konwalski Kikuë
Lavagnolli Thais
Mira-Bontenbal Hegias
Brown Karen E
Teng Grace
Carroll Tom
Terry Anna
Horan Katie
Marks Hendrik
Adams David J
Schatz David G
Aragon Luis
Fisher Amanda G
Krangel Michael S
Nasmyth Kim
Merkenschlager Matthias
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