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PMID: 1998343 Published · ppublish English Journal Article Research Support, Non-U.S. Gov't

A mutation in the second nucleotide binding fold of the cystic fibrosis gene.

American journal of human genetics ·Vol. 48 ·No. 3 ·1991-03-00 ·Pages 608-12

Osborne L, Knight R, Santis G, Hodson M

Abstract

The discovery last year of the deletion of a phenylalanine residue at amino acid position 508 of the cystic fibrosis (CF) gene has meant that approximately 70% of mutant chromosomes associated with CF can be accounted for. We report the finding of a substitution at nucleotide position 4041 of the CF gene, resulting in a change from asparagine to lysine at amino acid position 1303. We believe that this is a disease-causing mutation, as it involves a nonconservative amino acid change and has only been found on CF chromosomes with a consistent haplotype background. The mutation was detected using direct sequencing of PCR-amplified genomic DNA and was confirmed by dot hybridization to both normal and mutant allele-specific oligonucleotides. The mutation was detected on three chromosomes from four individuals but not on any normal chromosome. Its presence in the heterozygous state is not correlated with the clinical status of the individual patients.

MeSH Terms
Adult Alleles Base Sequence Cystic Fibrosis/genetics DNA/chemistry Exons Female Gene Amplification Gene Frequency Haplotypes Humans Male Molecular Sequence Data Mutation Pedigree
Chemicals
DNA
Authors & Affiliations
4 authors, click to expand affiliations / ORCID
Osborne L
Department of Cystic Fibrosis, National Heart and Lung Institute, London, England.
Knight R
Santis G
Hodson M
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18 references, click to expand
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Article Info
Journal
American journal of human genetics
Abbr.
Am J Hum Genet
ISSN
0002-9297
Published
1991-03-00
Pages
608-12
Language
English
Region
United States
NLM ID
0370475
PMCID
PMC1682979
Subset
IM
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