Abstract
A de novo alpha-synuclein A53T (p.Ala53 Th; c.209G > A) mutation has been identified in a Swedish family with autosomal dominant Parkinson's disease (PD). Two affected individuals had early-onset (before 31 and 40 years), severe levodopa-responsive PD with prominent dysphasia, dysarthria, and cognitive decline. Longitudinal clinical follow-up, EEG, SPECT and CSF biomarker examinations suggested an underlying encephalopathy with cortical involvement. The mutated allele (c.209A) was present within a haplotype different from that shared among mutation carriers in the Italian (Contursi) and the Greek-American Family H kindreds. One unaffected family member carried the mutation haplotype without the c.209A mutation, strongly suggesting its de novo occurrence within this family. Furthermore, a novel mutation c.488G > A (p.Arg163His; R163H) in the presenilin-2 (PSEN2) gene was detected, but was not associated with disease state.
MeSH Terms
Adult
Cerebral Cortex/pathology,physiopathology
Female
Humans
Intermediate Filament Proteins/genetics
Male
Mutation
Parkinson Disease/genetics,pathology,physiopathology
Pedigree
Polymerase Chain Reaction
Sweden
Chemicals
Intermediate Filament Proteins
desmuslin
Authors & Affiliations
18 authors, click to expand affiliations / ORCID
Puschmann Andreas
Department of Neurology, Lund University Hospital, Sweden; Department of Clinical Science, Section of Geriatric Psychiatry, Lund University, Sweden. andreas.puschmann@med.lu.se
Ross Owen A
Vilariño-Güell Carles
Lincoln Sarah J
Kachergus Jennifer M
Cobb Stephanie A
Lindquist Suzanne G
Nielsen Jørgen E
Wszolek Zbigniew K
Farrer Matthew
Widner Håkan
van Westen Danielle
Hägerström Douglas
Markopoulou Katerina
Chase Bruce A
Nilsson Karin
Reimer Jan
Nilsson Christer
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