Abstract
Polycythemia vera (PV) is a human clonal hematological disorder. The molecular etiology of the disease has not been identified. PV hematopoietic progenitor cells exhibit hypersensitivity to growth factors and cytokines, suggesting possible abnormalities in protein-tyrosine kinases and phosphatases. By sequencing the entire coding regions of cDNAs of candidate enzymes, we identified a G:C--> T:A point mutation of the JAK2 tyrosine kinase in 20 of 24 PV blood samples but none in 12 normal samples. The mutation has varying degrees of heterozygosity and is apparently acquired. It changes conserved Val(617) to Phe in the pseudokinase domain of JAK2 that is known to have an inhibitory role. The mutant JAK2 has enhanced kinase activity, and when overexpressed together with the erythropoietin receptor in cells, it caused hyperactivation of erythropoietin-induced cell signaling. This gain-of-function mutation of JAK may explain the hypersensitivity of PV progenitor cells to growth factors and cytokines. Our study thus defines a molecular defect of PV.
MeSH Terms
Amino Acid Sequence
Animals
Base Sequence
Cytokines/metabolism
DNA Mutational Analysis
DNA, Complementary/metabolism
Erythropoietin/metabolism
HeLa Cells
Heterozygote
Humans
Immunoblotting
Janus Kinase 2
Molecular Sequence Data
Mutation
Phenylalanine/chemistry
Point Mutation
Polycythemia Vera/genetics
Polymerase Chain Reaction
Protein Structure, Tertiary
Protein-Tyrosine Kinases/genetics,metabolism
Proto-Oncogene Proteins/genetics
Receptors, Erythropoietin/chemistry,metabolism
Sequence Analysis, DNA
Sequence Homology, Amino Acid
Signal Transduction
Transfection
Tyrosine/chemistry
Valine/chemistry
Chemicals
Cytokines
DNA, Complementary
Proto-Oncogene Proteins
Receptors, Erythropoietin
Erythropoietin
Tyrosine
Phenylalanine
Protein-Tyrosine Kinases
JAK2 protein, human
Janus Kinase 2
Valine
Authors & Affiliations
7 authors, click to expand affiliations / ORCID
Zhao Runxiang
Hematology/Oncology Division, Department of Medicine, Vanderbilt-Ingram Cancer Center, Vanderbilt University, Nashville, Tennessee 37232, USA.
Xing Shu
Li Zhe
Fu Xueqi
Li Qingshan
Krantz Sanford B
Zhao Zhizhuang Joe
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