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PMID: 15728840 Published · ppublish English Journal Article Research Support, N.I.H., Extramural Research Support, Non-U.S. Gov't Research Support, U.S. Gov't, P.H.S.

Parkin mediates nonclassical, proteasomal-independent ubiquitination of synphilin-1: implications for Lewy body formation.

Lim KL, Chew KC, Tan JM, Wang C, Chung KK, Zhang Y, Tanaka Y, Smith W, Engelender S, Ross CA, Dawson VL, Dawson TM

Abstract

It is widely accepted that the familial Parkinson's disease (PD)-linked gene product, parkin, functions as a ubiquitin ligase involved in protein turnover via the ubiquitin-proteasome system. Substrates ubiquitinated by parkin are hence thought to be destined for proteasomal degradation. Because we demonstrated previously that parkin interacts with and ubiquitinates synphilin-1, we initially expected synphilin-1 degradation to be enhanced in the presence of parkin. Contrary to our expectation, we found that synphilin-1 is normally ubiquitinated by parkin in a nonclassical, proteasomal-independent manner that involves lysine 63 (K63)-linked polyubiquitin chain formation. Parkin-mediated degradation of synphilin-1 occurs appreciably only at an unusually high parkin to synphilin-1 expression ratio or when primed for lysine 48 (K48)-linked ubiquitination. In addition we found that parkin-mediated ubiquitination of proteins within Lewy-body-like inclusions formed by the coexpression of synphilin-1, alpha-synuclein, and parkin occurs predominantly via K63 linkages and that the formation of these inclusions is enhanced by K63-linked ubiquitination. Our results suggest that parkin is a dual-function ubiquitin ligase and that K63-linked ubiquitination of synphilin-1 by parkin may be involved in the formation of Lewy body inclusions associated with PD.

MeSH Terms
Carrier Proteins/genetics,metabolism Catalysis Cell Line Gene Expression Humans Kidney Lewy Bodies/metabolism Lysine/chemistry Nerve Tissue Proteins/genetics,metabolism Parkinson Disease/metabolism Proteasome Endopeptidase Complex/metabolism Protein Processing, Post-Translational Recombinant Fusion Proteins/metabolism Synucleins Transfection Ubiquitin/metabolism Ubiquitin-Protein Ligases/biosynthesis,genetics,metabolism,physiology alpha-Synuclein
Chemicals
Carrier Proteins Nerve Tissue Proteins Recombinant Fusion Proteins SNCA protein, human SNCAIP protein, human Synucleins Ubiquitin alpha-Synuclein Ubiquitin-Protein Ligases parkin protein Proteasome Endopeptidase Complex Lysine
Authors & Affiliations
12 authors, click to expand affiliations / ORCID
Lim Kah Leong
Institute for Cell Engineering, Johns Hopkins University School of Medicine, Baltimore, Maryland 21205, USA.
Chew Katherine C M
Tan Jeanne M M
Wang Cheng
Chung Kenny K K
Zhang Yi
Tanaka Yuji
Smith Wanli
Engelender Simone
Ross Christopher A
Dawson Valina L
Dawson Ted M
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Article Info
Journal
The Journal of neuroscience : the official journal of the Society for Neuroscience
Abbr.
J Neurosci
ISSN
1529-2401
Published
2005-02-23
Pages
2002-9
Language
English
Region
United States
NLM ID
8102140
PMCID
PMC6726069
Subset
IM
Grants
NINDS NIH HHS · R01 NS048206 · United States
NINDS NIH HHS · P01 NS016375 · United States
NINDS NIH HHS · NS38377 · United States
NINDS NIH HHS · P50 NS038377 · United States
NINDS NIH HHS · NS16375 · United States
NINDS NIH HHS · NS48206 · United States
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