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PMID: 1083527 Published · ppublish English Journal Article Research Support, U.S. Gov't, P.H.S.

Molecular abnormality of human alpha1-antitrypsin variant (Pi-ZZ) associated with plasma activity deficiency.

Yoshida A, Lieberman J, Gaidulis L, Ewing C

Abstract

A human alpha1-antitrypsin variant protein was purified to homogeneity from homozygous variant subjects (Pi-ZZ) who had a deficiency of plasma trypsin inhibitory capacity. Molecular weight, specific trypsin inhibitory capacity, and immunologic activity of the variant protein were identical to those of normal. Amino acids, N-acetylglucosamine, and hexose contents were closely similar in the normal and variant proteins, but the sialic acid content in the variant protein was significantly lower than normal. The structural difference between the normal and the variant alpha1-antitrypsin was elucidated by fingerprinting of their tryptic peptides. Two amino acid substitutions, i.e., glutamic acid in the normal protein to lysine in the variant protein, and glutamic acid in the normal protein to glutamine in the variant protein, were found.

MeSH Terms
Amino Acids/analysis Carbohydrates/analysis Cross Reactions Genetic Variation Humans Isoelectric Point Molecular Weight Mutation Peptides/analysis alpha 1-Antitrypsin/analysis,blood alpha 1-Antitrypsin Deficiency
Chemicals
Amino Acids Carbohydrates Peptides alpha 1-Antitrypsin
Authors & Affiliations
4 authors, click to expand affiliations / ORCID
Yoshida A
Lieberman J
Gaidulis L
Ewing C
References (21)
21 references, click to expand
  1. Peptide separation by two-dimensional chromatography and electrophoresis.
    J Biol Chem. 1959 Nov;234:2897-900 PMID: 14404782
  2. PULMONARY EMPHYSEMA AND ALPHA1-ANTITRYPSIN DEFICIENCY.
    Acta Med Scand. 1964 Feb;175:197-205 PMID: 14124635
  3. STRUCTURAL REQUIREMENTS OF SPECIFIC SUBSTRATES FOR GUINEA PIG LIVER TRANSGLUTAMINASE.
    J Biol Chem. 1965 Jul;240:2951-60 PMID: 14342319
  4. DISC ELECTROPHORESIS. II. METHOD AND APPLICATION TO HUMAN SERUM PROTEINS.
    Ann N Y Acad Sci. 1964 Dec 28;121:404-27 PMID: 14240539
  5. The preparation and enzymatic hydrolysis of reduced and S-carboxymethylated proteins.
    J Biol Chem. 1963 Feb;238:622-7 PMID: 14023808
  6. The thiobarbituric acid assay of sialic acids.
    J Biol Chem. 1959 Aug;234(8):1971-5 PMID: 13672998
  7. Determination of serum glycoproteins.
    Methods Biochem Anal. 1955;2:279-311 PMID: 14393571
  8. Protein measurement with the Folin phenol reagent.
    J Biol Chem. 1951 Nov;193(1):265-75 PMID: 14907713
  9. Alpha 1 -antitrypsin (A1AT) accumulation in livers of emphysematous patients with A1AT deficiency.
    Hum Pathol. 1972 Sep;3(3):361-70 PMID: 4114796
  10. Purification and properties of normal human alpha 1-antitrypsin.
    Arch Biochem Biophys. 1973 May;156(1):215-22 PMID: 4125886
  11. Letter: Defect in alpha1-antitrypsin deficiency.
    Lancet. 1973 Oct 13;2(7833):844-5 PMID: 4126636
  12. Heterozygous and homozygous alpha1-antitrypsin deficiency in patients with pulmonary emphysema.
    N Engl J Med. 1969 Aug 7;281(6):279-84 PMID: 4183173
  13. Cirrhosis associated with alpha-1-antitrypsin deficiency: a previously unrecognized inherited disorder.
    J Lab Clin Med. 1969 Jun;73(6):934-9 PMID: 4182334
  14. Purification and partial characterization of pas-positive inclusion bodies from the liver in alpha 1-antitrypsin deficiency.
    N Engl J Med. 1975 Jan 23;292(4):176-80 PMID: 45843
  15. Identification and characteristics of the common alpha 1 -antitrypsin phenotypes.
    Chest. 1972 Nov;62(5):557-64 PMID: 4628260
  16. Basis of the defect in alpha-1-antitrypsin deficiency.
    Nature. 1973 Jun 15;243(5407):410-1 PMID: 4542721
  17. Pathogenesis of deficient serum alpha1-antitrypsin in the type ZZ homozygote.
    Biochem Genet. 1974 Sep;12(3):235-42 PMID: 4548648
  18. Characterization of alpha1-antitrypsin in the inclusion bodies from the liver in alpha 1-antitrypsin deficiency.
    N Engl J Med. 1975 Sep 18;293(12):576-9 PMID: 168490
  19. Molecular basis for the alpha1-protease inhibitor deficiency.
    Nature. 1975 May 15;255(5505):240-1 PMID: 1079921
  20. The reliability of molecular weight determinations by dodecyl sulfate-polyacrylamide gel electrophoresis.
    J Biol Chem. 1969 Aug 25;244(16):4406-12 PMID: 5806584
  21. Quantitative estimation of proteins by electrophoresis in agarose gel containing antibodies.
    Anal Biochem. 1966 Apr;15(1):45-52 PMID: 5959431
Article Info
Journal
Proceedings of the National Academy of Sciences of the United States of America
Abbr.
Proc Natl Acad Sci U S A
ISSN
0027-8424
Published
1976-04-00
Pages
1324-8
Language
English
Region
United States
NLM ID
7505876
PMCID
PMC430262
Subset
IM
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